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Adenomyosis in a uterine horn of a patient with Mayer-Rokitansky-Kuster-Hauser syndrome
  1. Ana Marta Pinto1,
  2. Ana Cláudia Santos1,2,
  3. Nuno Oliveira1 and
  4. Mário Oliveira1
  1. 1Obstetrics and Gynaecology, Centro Hospitalar do Baixo Vouga, EPE, Aveiro, Portugal
  2. 2Obstetrics and Gynaecology, Centro Hospitalar e Universitário de Coimbra, EPE, Coimbra, Portugal
  1. Correspondence to Dr Ana Marta Pinto; anamartapinto91{at}


A 37-year-old woman with a previous diagnosis of Mayer-Rokitansky-Kuster-Hauser syndrome at 18 years of age was referred from a primary healthcare physician to a gynaecology appointment in our centre. She presented with a 2-year worsening pelvic pain and dyspareunia, symptoms that were previously absent and, at the time, with inadequate relief with oral analgesia. Physical examination showed absent uterine cervix and hypoplastic superior vagina. Transvaginal ultrasound and MRI suggested the presence of an hypoplasic uterus in left rotation. Laparoscopically, two asymmetric rudimentary horns were found, united by a fibrous central band, with an enlarged and congestive left horn. The three structures were removed as a whole. Histopathological examination reported the presence of multiple adenomyotic foci along the full thickness of the left rudimentary horn. The patient had an uneventful postoperative recovery and full remission of her symptoms.

  • obstetrics and gynaecology
  • surgery

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  • Contributors All authors have read and approved the manuscript. All authors contributed to the work according to ICMJE requirements for authorship. All authors declare that the manuscript is an original work that has not been submitted to another journal or conference. AMP was responsible for planning, conception, bibliographic research, reporting and design. ACS brought essential contributions and revised the manuscript. MO and NO supervised the whole work and revised the manuscript.

  • Funding The authors have not declared a specific grant for this research from any funding agency in the public, commercial or not-for-profit sectors.

  • Case reports provide a valuable learning resource for the scientific community and can indicate areas of interest for future research. They should not be used in isolation to guide treatment choices or public health policy.

  • Competing interests None declared.

  • Provenance and peer review Not commissioned; externally peer reviewed.