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Maxillary unicystic ameloblastoma: a rare presentation
  1. Ryo Imase1 and
  2. Takuma Watanabe2
  1. 1Department of Oral and Maxillofacial Surgery, Uwajima City Hospital, Uwajima, Japan
  2. 2Department of Oral and Maxillofacial Surgery, Kyoto University, Kyoto, Japan
  1. Correspondence to Dr Takuma Watanabe; takuma{at}


Unicystic ameloblastoma (UAM), a rare variant of ameloblastoma, is an odontogenic epithelial neoplasm typically appearing in the mandible. We report an extremely rare case of maxillary UAM with an impacted canine and supernumerary tooth. The patient was a woman in her late 30s who presented with a slight expansion of the left anterior maxilla due to a cystic lesion with impacted teeth. Under a clinical diagnosis of dentigerous cyst, the cystic lesion was completely enucleated by extracting the impacted teeth. Based on the clinical features and pathological findings, the final diagnosis was intraluminal UAM in the anterior maxilla. In the present case, despite the rarity of UAM with impacted teeth in the anterior maxilla, it should be considered during differential diagnosis. Careful clinical examination is required for diagnostic accuracy since the clinical findings of tooth-containing ameloblastoma and dentigerous cyst are very similar.

  • Dentistry and oral medicine
  • Pathology
  • Oral and maxillofacial surgery

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  • Contributors RI and TW wrote up the case report and performed a literature review on maxillary unicystic ameloblastoma.

  • Funding The authors have not declared a specific grant for this research from any funding agency in the public, commercial or not-for-profit sectors.

  • Case reports provide a valuable learning resource for the scientific community and can indicate areas of interest for future research. They should not be used in isolation to guide treatment choices or public health policy.

  • Competing interests None declared.

  • Provenance and peer review Not commissioned; externally peer reviewed.