Oligodendrogliomas are the third most common type of glioma. Oligodendrogliomas are typically indolent tumours, yet the majority of them are incurable and most patients will ultimately die. Anaplastic oligodendrogliomas are important to recognise from other primary brain tumours, since they have unique molecular, histological and clinical features. Oligodendroglioma, especially the anaplastic type, has a tendency to intracranial and extracranial metastasis. In this paper, we present an unusual manifestation of anaplastic oligodendroglioma.