Summary

The authors report a rare case of lingual thyroglossal duct cyst (TGDC) which is being treated by non-conventional technique of intraoral marsupialisation and the authors also review the embryology of TGDC and its diagnosis. The patient was operated upon by intraoral route and the cyst was marsupialised. There is no recurrence in the past 2-year follow-up. This approach avoids unnecessary scar and postoperative morbidity associated with opening neck planes and removing the central hyoid as indicated in conventional technique.